KEGG   VARIANT: 1778v1
Entry
1778v1                      Variant                                
Name
DYNC1H1 mutation
Type
Loss of function
Gene
DYNC1H1  dynein cytoplasmic 1 heavy chain 1 [KO:K10413]
Organism
hsa_var Human gene variants (Homo sapiens)
Variation
mutations
OmimVar: 600112
Network
nt06515  Regulation of kinetochore-microtubule interactions
nt06541  Cytoskeleton in neurons
Disease
H00264  Charcot-Marie-Tooth disease
H00455  Spinal muscular atrophy
H00773  Autosomal dominant intellectual developmental disorder
H01881  Complex cortical dysplasia with other brain malformations
Reference
  Authors
Weedon MN, Hastings R, Caswell R, Xie W, Paszkiewicz K, Antoniadi T, Williams M, King C, Greenhalgh L, Newbury-Ecob R, Ellard S
  Title
Exome sequencing identifies a DYNC1H1 mutation in a large pedigree with dominant axonal Charcot-Marie-Tooth disease.
  Journal
Am J Hum Genet 89:308-12 (2011)
DOI:10.1016/j.ajhg.2011.07.002
Reference
  Authors
Willemsen MH, Vissers LE, Willemsen MA, van Bon BW, Kroes T, de Ligt J, de Vries BB, Schoots J, Lugtenberg D, Hamel BC, van Bokhoven H, Brunner HG, Veltman JA, Kleefstra T
  Title
Mutations in DYNC1H1 cause severe intellectual disability with neuronal migration defects.
  Journal
J Med Genet 49:179-83 (2012)
DOI:10.1136/jmedgenet-2011-100542
Reference
  Authors
Harms MB, Ori-McKenney KM, Scoto M, Tuck EP, Bell S, Ma D, Masi S, Allred P, Al-Lozi M, Reilly MM, Miller LJ, Jani-Acsadi A, Pestronk A, Shy ME, Muntoni F, Vallee RB, Baloh RH
  Title
Mutations in the tail domain of DYNC1H1 cause dominant spinal muscular atrophy.
  Journal
Neurology 78:1714-20 (2012)
DOI:10.1212/WNL.0b013e3182556c05
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